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Protocol Details

Screening and Natural History of Patients with Polyostotic Fibrous Dysplasia and the McCune-Albright Syndrome

This study is currently recruiting participants.

Summary | Eligibility | Citations | Contacts

Summary

Number

98-D-0145

Sponsoring Institute

National Institute of Dental And Craniofacial Research (NIDCR)

Recruitment Detail

Type: Participants currently recruited/enrolled
Gender: Male & Female
Min Age: 1 days
Max Age: 100 Years

Referral Letter Required

No

Population Exclusion(s)

None

Keywords

Fibrous Dysplasia (FD);
McCune-Albright Syndrome (MAS);
Natural History

Recruitment Keyword(s)

None

Condition(s)

McCune-Albright Syndrome

Investigational Drug(s)

None

Investigational Device(s)

None

Intervention(s)

None

Supporting Site

National Institute of Dental and Craniofacial Research

Polyostotic fibrous dysplasia (PFD) is a sporadic disorder which affects multiple sites in the skeleton. The bone at these sites is rapidly resorbed and replaced by abnormal fibrous tissue or mechanically abnormal bone. PFD may occur alone or as part of the McCune-Albright Syndrome (MAS), a syndrome originally defined by the triad of PFD, cafe-au-lait pigmentation of the skin, and precocious puberty. The bony lesions are frequently disfiguring, disabling and painful, and depending on the location of the lesion, can cause significant morbidity. Lesions in weight-bearing bones can lead to disabling fractures, while lesions in the skull can lead to compression of vital structures such as cranial nerves.

The natural history of this disease is poorly described and there are no clearly defined systemic therapies for the bone disease. This is a data collection and specimen acquisition protocol. The purpose of the study is to define the natural history of the disease by following PFD/MAS subjects over time and by using in vitro experimentation with samples/tissue from subjects with the disease.

Study Objectives

1) Primary Objective

Define the natural history of disease by gaining clinical and basic information about PFD/MAS by following subjects clinically and using in vitro experimentation with tissue from subjects with the disease.

2) Secondary Objective

Refer eligible subjects for enrollment into other appropriate research protocols, if any are currently active.

Study Population

The study population will include:

1. Subjects with known or suspected Polyostotic Fibrous Dysplasia (PFD) or in combination with McCune-Albright Syndrome (MAS)

2. Subjects who meet eligibility criteria will be accepted regardless of gender, race, or ethnicity

Design

This study is an observational/natural history study of PFD/MAS.

Outcome Measures

Primary

1) Successfully enroll subjects with PFD or MAS for the collection, evaluation and analysis of data obtained from clinical visits.

2) Obtain onsite and offsite research tissue (waste tissue) from patients with PFD/MAS that are enrolled onto this study or from individuals with PFD/MAS that are offsite and willing to donate waste tissue to NIH. Research tissue will be used with existing primary cell culture technology (ongoing in our laboratories) to:

-understand the basic bone biology of the pathologic cell (or cells) involved in the lesions of PFD/MAS

- determine the presence or absence of mutated cells at "uninvolved sites" to formulate better strategies of predicting the initiation of new lesions, the natural history of lesion progression and/or response to therapy

- understand osteogenic differentiation, in particular, the role of G(s)alpha in these lesions, which will be transferable to our understanding of bone biology in general

- understand the pathophysiology of FD and/or endocrine lesions

- develop better methods of identifying and expanding unaffected bone cells from patients with PFD in an effort to create better grafting material(s)

3) Identify and predict clinical and biological behavior of fibrous dysplastic bone lesions based on:

- stability, rate of growth, rate of change, progression and regression, and development of new lesions

- differences between cranial, axial and appendicular lesions

4) Define the natural history of the multiple endocrinopathies associated with MAS and the response to standard of care medications

5) Define clinical and biological aspects of the disease not previously identified

6) Generate future research studies related to PFD alone or in combination with MAS

Secondary

1) Successfully enroll eligible subjects into active research protocols applicable to the FD/MAS population.

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Eligibility

INCLUSION CRITERIA

1. Any patient, age 1 day of life and older, with a likelihood of having PFD or MAS, based on information from an appropriate referring physician or surgeon or provided by the patient or guardian. The diagnosis will be based on typical findings on bone biopsy or on clinical grounds.

EXCLUSION CRITERIA

1. Patient, child or parent/guardian unwilling to fully cooperate with the evaluations.

2. Patient or parent/guardian unable to provide informed consent.


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Citations:

Not Provided

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Contacts:

Principal Investigator

Referral Contact

For more information:

Alison M. Boyce, M.D.
National Institute of Dental And Craniofacial Research (NIDCR)
NIHBC 30 BG RM 218
30 CONVENT DR
BETHESDA MD 20892
(301) 827-4802
alison.boyce@nih.gov

Olivia J. de Jong, C.R.N.P.
National Institute of Dental And Craniofacial Research (NIDCR)
NIHBC 10 - CLINICAL CENTER BG RM 1N118
10 CENTER DR
BETHESDA MD 20892
(240) 595-2764
olivia.dejong@nih.gov

Office of Patient Recruitment
National Institutes of Health Clinical Center (CC)
Building 61, 10 Cloister Court
Bethesda, Maryland 20892
Toll Free: 1-800-411-1222
Local Phone: 301-451-4383
TTY: TTY Users Dial 7-1-1
ccopr@nih.gov

Clinical Trials Number:

NCT00001727

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